Massively Parallel Sequencing
If a familial sequence variant has been previously identified, targeted sequencing for that variant may be appropriate; refer to the Laboratory Test Directory for additional information.
Inherited cardiomyopathy and arrhythmia disorders are genetically and phenotypically heterogeneous. Phenotypes include arrhythmogenic right ventricular cardiomyopathy (ARVC), Brugada syndrome (BrS), catecholaminergic polymorphic ventricular tachycardia (CPVT), dilated cardiomyopathy (DCM), hypertrophic cardiomyopathy (HCM), left ventricular noncompaction (LVNC), long QT syndrome (LQTS), and short QT syndrome (SQTS). Molecular testing is used to determine if a genetic etiology can be identified, which can facilitate patient management and screening of at-risk relatives.
Disease Overview
See Common Disorders table below.
Genetics
See Genes Tested table for genes included in the panel.
Test Interpretation
Methodology
This test is performed using the following sequence of steps:
- Selected genomic regions, primarily coding exons and exon-intron boundaries, from the targeted genes are isolated from extracted genomic DNA using a probe-based hybrid capture enrichment workflow.
- Enriched DNA is sequenced by massively parallel sequencing (MPS; also known as next generation sequencing, or NGS) followed by paired-end read alignment and variant calling using a custom bioinformatics pipeline. The pipeline includes an algorithm for the detection of large deletions and duplications.
- Sanger sequencing is performed as necessary to fill in regions of low coverage and in certain situations, to confirm variant calls.
- Large deletion/duplication calls made using MPS are confirmed by an orthogonal exon-level microarray when sample quality and technical conditions allow.
Clinical Sensitivity
Variable, dependent on phenotype/condition
- ARVC: 50%
- BrS: 15-30%
- CPVT: 60%
- DCM: 25-40% for familial DCM, 10-25% for isolated DCM
- HCM: 50-60% for familial HCM, 20-30% for isolated HCM
- LQTS: 60-75%
Analytic Sensitivity
Variant Class | Analytic Sensitivity (PPA) Estimatea (%) and 95% Credibility Region | Analytic Specificity (NPA) |
---|---|---|
SNVs | >99 (96.9-99.4) | >99.9 |
Deletions 1-10 bpb | 93.8 (84.3-98.2) | >99.9 |
Insertions 1-10 bpb | 94.8 (86.8-98.5) | >99.9 |
Exon-levelc deletions | 97.8 (90.3-99.8) [2 exons or larger] 62.5 (38.3-82.6) [single exon] | >99.9 |
Exon-levelc duplications | 83.3 (56.4-96.4) [3 exons or larger] | >99.9 |
aGenes included on this test are a subset of a larger methods-based validation from which the PPA values are derived. These values do not apply to testing performed by multiplex ligation-dependent probe amplification (MLPA). bVariants greater than 10 bp may be detected, but the analytic sensitivity may be reduced. cIn most cases, a single exon deletion or duplication is less than 450 bp and 3 exons span a genomic region larger than 700 bp. bp, base pairs; PPA, positive percent agreement; NPA, negative percent agreement; SNVs, single nucleotide variants |
Limitations
- A negative result does not exclude a heritable form of cardiomyopathy or arrhythmia.
- Diagnostic errors can occur due to rare sequence variations.
- Interpretation of this test result may be impacted if the individual has had an allogeneic stem cell transplantation.
- The following will not be evaluated:
- Variants outside the coding regions and intron-exon boundaries of the targeted genes
- Variants in the mitochondrial genome
- Regulatory region and deep intronic variants
- Deletions/duplications in PTPN11
- Breakpoints of large deletions/duplications
- SNVs and small deletions/insertions will not be called in the following exons due to technical limitations of the assay:
- BRAF (NM_004333) exon(s) 5,18
- BRAF (NM_001354609) exon(s) 5,18,19
- BRAF (NM_001374244) exon(s) 5,10,19
- BRAF (NM_001374258) exon(s) 5,10,19,20
- BRAF (NM_001378467) exon(s) 5,18,19
- BRAF (NM_001378468) exon(s) 5,18
- BRAF (NM_001378469) exon(s) 5,18
- BRAF (NM_001378470) exon(s) 4,17,18
- BRAF (NM_001378471) exon(s) 5,17,18
- BRAF (NM_001378472) exon(s) 5,18,19
- BRAF (NM_001378473) exon(s) 5,18
- BRAF (NM_001378474) exon(s) 5,18
- BRAF (NM_001378475) exon(s) 4,17,18
- CALM1 (NM_001363670) exon(s) 1
- CSRP3 (NM_001369404) partial exon(s) 5(Chr11:19204180-19204196)
- DES (NM_001382712) exon(s) 9
- FKTN (NM_001351497) exon(s) 6
- FKTN (NM_001351498) partial exon(s) 9(Chr9:108382363-108382373)
- FLNC (NM_001458) exon(s) 47,48
- FLNC (NM_001127487) exon(s) 46,47
- PRKAG2 (NM_016203) exon(s) 13
- PRKAG2 (NM_001040633) exon(s) 13
- PRKAG2 (NM_001304527) exon(s) 11
- PRKAG2 (NM_001304531) exon(s) 10
- PRKAG2 (NM_001363698) exon(s) 11
- PRKAG2 (NM_024429) exon(s) 9
- RAF1 (NM_001354689) exon(s) 8
- RAF1 (NM_001354694) exon(s) 7
- SOS1 (NM_001382394) exon(s) 1
- TECRL (NM_001363796) exon(s) 12
- TPM1 (NM_001365777) partial exon(s) 9(Chr15:63358119-63358186)
- TPM1 (NM_001365780) partial exon(s) 8(Chr15:63358119-63358186)
- TTN (NM_001267550) exon(s) 172,173,174,175,176,177,178,179,180,181,182,183,184,185,186,187,188,189,190,191,192,193,194,195,196,197
- TTN (NM_001256850) exon(s) 154,155,156
- TTN (NM_133378) exon(s) 153,154,155
- The following may not be detected:
- Deletions/duplications/insertions of any size by massively parallel sequencing
- Large duplications less than 3 exons in size
- Noncoding transcripts
- Some variants due to technical limitations in the presence of pseudogenes, repetitive, or homologous regions
- Low-level somatic variants
Common Disorders
Genes Tested
Gene | MIM Number | Disorder | Inheritance |
---|---|---|---|
ABCC9 | 601439 | Cantu syndrome DCM 10 Familial atrial fibrillation 12 | AD |
ACTC1 | 102540 | HCM 11 Atrial septal defect 5 DCM 1R | AD |
ACTN2 | 102573 | DCM 1AA with or without LVNC HCM 23 with or without LVNC | AD |
AGL | 610860 | Glycogen storage disease IIIa or IIIb | AR |
ALMS1 | 606844 | Alstrom Syndrome | AR |
ALPK3 | 18052 | HCM 27 | AR |
BAG3 | 603883 | Myofibrillar myopathy 6 DCM 1HH | AD |
BRAF | 164757 | Cardiofaciocutaneous syndrome 1 Noonan syndrome 7 | AD |
CACNA1C | 114205 | Timothy syndrome LGTS 8 | AD |
CALM1 | 114180 | LQTS 14 CPVT 4 | AD |
CALM2 | 114182 | LQTS 15 CPVT | AD |
CALM3 | 114183 | LQTS 16 CPVT 6 | AD |
CASQ2 | 114251 | CPVT 2 | AR |
CAV3 | 601253 | Familial hypertrophic cardiomyopathy, 1 Long QT syndrome 9 | AD |
CRYAB | 123590 | Myofibrillar myopathy, 2 DCM 1II | AD |
Myofibrillar myopathy, fatal infantile hypertonic, alpha-B crystallin-related | AR | ||
CSRP3 | 600824 | HCM 12 | AD |
DES | 125660 | Myofibrillar myopathy, 1 | AD/AR |
DCM 1I | AD | ||
DMD | 300377 | Becker muscular dystrophy DCM 3B Duchenne muscular dystrophy | XL |
DOLK | 610746 | Congenital disorder of glycosylation Im | AR |
DSC2 | 125645 | ARVC 11 | AD |
ARVC 11 with mild palmoplantar keratoderma and woolly hair | AR | ||
DSG2 | 125671 | ARVC 10 DCM 1BB | AD |
DSP | 125647 | ARVC 8 DCM with woolly hair, keratoderma, and tooth agenesis | AD |
DCM with woolly hair and keratoderma | AR | ||
EMD | 300384 | Emery-Dreifuss muscular dystrophy 1 | XL |
FHL1 | 300163 | Uruguay faciocardiomusculoskeletal syndrome Scapuloperoneal myopathy Myopathy with postural muscle atrophy Emery-Dreifuss muscular dystrophy 6 Reducing body myopathy 1B | XL |
FKTN | 607440 | DCM 1X Muscular dystrophy-dystroglycanopathy Ad4 | AR |
FLNC | 102565 | Myofibrillar myopathy 5 HCM 26 Restrictive cardiomyopathy 5 Distal myopathy 4 | AD |
GAA | 606800 | Glycogen storage disease II | AR |
GLA | 300644 | Fabry disease | XL |
HCN4 | 605206 | Sick sinus syndrome 2 | AD |
HRAS | 190020 | Costello syndrome | AD |
JPH2 | 605267 | HCM 17 | AD |
JUP | 173325 | ARVC 12 | AD |
Naxos disease | AR | ||
KCNE1 | 176261 | LQTS 5 | AD |
Jervell and Lange-Nielsen syndrome 2 | AR | ||
KCNE2 | 603796 | Familial atrial fibrillation 4 LQTS 6 | AD |
KCNH2 | 152427 | LQTS 2 SQTS 1 | AD |
KCNJ2 | 600681 | Andersen syndrome SQTS 3 Familial atrial fibrillation 9 | AD |
KCNQ1 | 607542 | LQT S 1 Familial atrial fibrillation 3 SQTS 2 | AD |
Jervell and Lange-Nielsen syndrome 1 | AR | ||
KRAS | 190070 | Cardiofaciocutaneous syndrome 2 Noonan syndrome 3 | AD |
LAMP2 | 309060 | Danon disease | XL |
LDB3 | 605906 | DCM 1C with or without LVNC Myofibrillar myopathy, 4 | AD |
LMNA | 150330 | DCM 1A Emery-Dreifuss muscular dystrophy 2 Slovenian type heart-hand syndrome Congenital muscular dystrophy Malouf syndrome | AD |
Emery-Dreifuss muscular dystrophy 3 | AR | ||
MAP2K1 | 176872 | Cardiofaciocutaneous syndrome 3 | AD |
MAP2K2 | 601263 | Cardiofaciocutaneous syndrome 4 | AD |
MYBPC3 | 600958 | HCM 4 DCM 1MM LVNC 10 | AD |
MYH6 | 160710 | DCM 1EE Sick sinus syndrome 3 Atrial septal defect 3 | AD |
MYH7 | 160760 | DCM 1S HCM 1 Laing distal myopathy | AD |
Myosin storage myopathy | AR | ||
MYL2 | 160781 | HCM 10 | AD |
MYL3 | 160790 | HCM 8 | AD/AR |
NEXN | 613121 | DCM 1CC | AD |
NKX2-5 | 600584 | Atrial septal defect with or without AV conduction defects | AD |
NRAS | 164790 | Noonan syndrome 6 | AD |
PKP2 | 602861 | ARVC 9 | AD |
PLN | 172405 | DCM 1P HCM 18 | AD |
PRDM16 | 605557 | DCM 1LL | AD |
PRKAG2 | 602743 | HCM 6 Glycogen storage disease of the heart, lethal congenital Wolff-Parkinson-White syndrome | AD |
PTPN11 | 176876 | Noonan syndrome 1 LEOPARD syndrome 1 | AD |
RAF1 | 164760 | Noonan syndrome 5 DCM 1NN LEOPARD syndrome 2 | AD |
RBM20 | 613171 | DCM 1DD | AD |
RIT1 | 609591 | Noonan syndrome 8 | AD |
RYR2 | 180902 | ARVC 2 CPVT 1 | AD |
SCN5A | 600163 | Brugada syndrome 1 DCM 1E Familial atrial fibrillation 10 Familial heart block Familial paroxysmal ventricular fibrillation LQTS 3 | AD |
Sick sinus syndrome 1 | AR | ||
SOS1 | 182530 | Noonan syndrome 4 | AD |
TAFAZZIN | 300394 | Barth syndrome | XL |
TCAP | 604488 | Limb-girdle muscular dystrophy 2G | AR |
TECRL | 617242 | CPVT 3 | AR |
TMEM43 | 612048 | ARVC 5 Emery-Dreifuss muscular dystrophy 7 | AD |
TNNC1 | 191040 | DCM 1Z HCM 13 | AD |
TNNI3 | 191044 | DCM 1FF Restrictive cardiomyopathy 1 HCM 7 | AD |
DCM 2A | AR | ||
TNNI3K | 613932 | Cardiac conduction disease with or without DCM | AD |
TNNT2 | 191045 | HCM 2 DCM 1D Restrictive cardiomyopathy 3 | AD |
TPM1 | 191010 | HCM 3 DCM 1Y | AD |
TRDN | 603283 | Cardiac arrhythmia syndrome with or without skeletal muscle weakness | AR |
TTN | 188840 | DCM 1G Myofibrillar myopathy 9 | AD |
Salih myopathy | AR | ||
TTR | 176300 | Transthyretin-related amyloidosis | AD |
VCL | 193065 | DCM 1W | AD |
AD, autosomal dominant; AR, autosomal recessive, XL, X-linked |
References
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GeneReviews - Arrhythmogenic Right Ventricular Cardiomyopathy
McNally E, MacLeod H, Dellefave-Castillo L. Arrhythmogenic right ventricular cardiomyopathy. In: Adam MP, Ardinger HH, Pagon RA, et al, eds. GeneReviews. University of Washington, Seattle. Updated May 2017; accessed Mar 2022.
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GeneReviews - Brugada Syndrome
Brugada R, Campuzano O, Sarquella-Brugada G, et al. Brugada syndrome. In: Adam MP, Ardinger HH, Pagon RA, et al, eds. GeneReviews. University of Washington, Seattle. Updated Nov 2016; accessed Mar 2022.
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GeneReviews - Catecholaminergic Polymorphic Ventricular Tachycardia
Napolitano C, Priori SG, Bloise R. Catecholaminergic polymorphic ventricular tachycardia. In: Adam MP, Ardinger HH, Pagon RA, et al, eds. GeneReviews. University of Washington, Seattle. Updated Oct 2016; accessed Mar 2022.
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29567486
Hershberger RE, Givertz MM, Ho CY, et al. Genetic evaluation of cardiomyopathy–a Heart Failure Society of America practice guideline. J Card Fail. 2018;24(5):281-302.
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GeneReviews - Hypertrophic Cardiomyopathy Overview
Cirino AL, Ho C. Hypertrophic cardiomyopathy overview. In: Adam MP, Ardinger HH, Pagon RA, et al, eds. GeneReviews. University of Washington, Seattle. Updated Jun 2021; accessed Mar 2022.
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GeneReviews - Long QT Syndrome
Alders M, Bikker H, Christiaans I. Long QT syndrome. In: Adam MP, Ardinger HH, Pagon RA, et al, eds. GeneReviews. University of Washington, Seattle. Updated Feb 2018; accessed Mar 2022.
Use to confirm the hereditary form of cardiomyopathy or arrhythmia.